Choristoma is described as the growth of normal tissue in an unusual location. Intraoral choristoma may be comprised of various tissue types such as cartilage, bone, gastric mucosa and, even glial tissue. Osseous choristoma is a rare, benign normal bony tissue in an abnormal location, commonly over the dorsum of the tongue though cases at maxillofacial region have been reported. This entity should be kept in mind because it can be confused with other tumor and tumor-like lesions of the tongue. We report a case of lingual osseous choristoma along with discussion regarding its epidemiology, pathogenesis, clinical features, and treatment.